Directly repeated sequences associated with pathogenic mitochondrial DNA deletions.

نویسندگان

  • D R Johns
  • S L Rutledge
  • O C Stine
  • O Hurko
چکیده

We determined the nucleotide sequences of junctional regions associated with large deletions of mitochondrial DNA found in four unrelated individuals with a phenotype of chronic progressive external ophthalmoplegia. In each patient, the deletion breakpoint occurred within a directly repeated sequence of 13-18 base pairs, present in different regions of the normal mitochondrial genome-separated by 4.5-7.7 kilobases. In two patients, the deletions were identical. When all four repeated sequences are compared, a consensus sequence of 11 nucleotides emerges, similar to putative recombination signals, suggesting the involvement of a recombinational event. Partially deleted and normal mitochondrial DNAs were found in all tissues examined, but in very different proportions, indicating that these mutations originated before the primary cell layers diverged.

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عنوان ژورنال:
  • Proceedings of the National Academy of Sciences of the United States of America

دوره 86 20  شماره 

صفحات  -

تاریخ انتشار 1989